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도미영,김희만,고영국,임승길,정제헌,정남식,김연아,강신애,문재훈,이진형,최상태 대한내분비학회 2005 Endocrinology and metabolism Vol.20 No.3
A pheochromocytoma is a catecholamine secreting tumor, which is often overlooked when cardiovascular complications, such as acute heart failure, myocardial infarction, angina pectoris, arrhythmias, and dilated cardiomyopathy, presented as the initial clinical manifestations. Failure to identify a pheochromocytoma in these situations may be fatal.We report the case of 32-year-old female, who presented with cardiogenic shock. Echocardiography revealed severe global hypokinesia of the dilated left ventricle, with the exception of the apex. Computed tomography of the aorta showed a well-enhanced left adrenal mass, 3.5cm in diameter. A 24 hour urine collection study for catecholamines and a 131I-metaiodobenzylguanidine(MIBG) scan were suggestive of the diagnosis of a single adrenal pheochromocytoma. The patient stabilized after shock management, and recovered with intensive medical treatment. Follow-up echocardiography revealed normalized cardiac function and chamber dimensions. Thereafter, the adrenal mass was successfully removed using laparaoscopic surgery, without complications 갈색세포종이 급성심부전, 심근경색, 협심증, 부정맥, 심인성 쇼크와 같은 합병증으로 처음 발현되는 경우 진단이 어렵고 늦어지게 된다. 저자들은 고혈압과 중증의 심부전, 심인성 쇼크가 동반된 젊은 여자에서 갈색세포종이 진단되어 쇼크에 대한 고식적 처치와 적극적인 약물치료, 그리고 수술적 제거로 갈색세포종과 동반된 카테콜라민에 의한 심근근육병증 및 심부전이 가역적으로 회복되었기에 보고하는 바이다.