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어린선과 동반된 건선을 Ustekinumab으로 치료한 1예
국형돈,배주윤,이동헌,정혜정,박미연,안지영 대한건선학회 2021 대한건선학회지 Vol.18 No.2
A 50-year-old man was being treated for psoriasis and X-linked recessive ichthyosis. The onset of psoriasis was 30 years ago, and X-linked recessive ichthyosis was reported to occur immediately after birth. He had psoriasis lesions of scaly erythematous plaque and ichthyosis lesions of finescale patches on the whole body. Psoriasis and ichthyosis were treated with conventional treatment, but they did not show effect. With the start of Ustekinumab, psoriasis, as well as ichthyosis lesions, improved. When the patient was scheduled to take the fifth injection, he visited the clinic one month later than the scheduled date, both psoriasis and ichthyosis lesions were worsened again. Re-administration of Ustekinumab improved both disease lesions. Herein, we report a case of psoriasis accompanied by X-linked recessive ichthyosis as an interesting case of improvement of both diseases in Ustekinumab treatment.
Cutaneous Adverse Reaction After COVID-19 Vaccination
국형돈,안지영,정혜정 대한의진균학회 2022 대한의진균학회지 Vol.27 No.3
As coronavirus disease 2019 (COVID-19) spreads worldwide, various vaccines are being developed against the SARS-CoV-2 virus. These vaccines had to be developed in a relatively short period; therefore, they had to be manufactured using a method different from that of conventional vaccines. In addition, many people were vaccinated in a short period, and various side effects related to vaccination have been reported. In this article, we describe the injection site reactions and some unique skin reactions associated with COVID-19 vaccination, such as drug eruptions, bullous lesions, and foreign body reactions, with their possible causes.
A Case of Successful Bare Metal Stenting for Aortic Coarctation in an Adult
국형돈,나승운,Dong Hyeok Kim,이선기,Suk-Kyu Oh,Tae Hoon Ahn,Won Heum Shim,Woohyeun Kim 대한심장학회 2013 Korean Circulation Journal Vol.43 No.4
Aortic coarctation is a correctable hypertensive disease. For safety reasons and due to the invasiveness of surgical techniques, percutane-ous interventions have become drastically more popular in recent times. In elderly patients with aortic coarctation who are at risk of an aortic wall aneurysm and rupture, covered stents are preferred but in younger patients, bare metal stenting may be sufficient for long-term safety. Herein we present a 47-year-old typical aortic coarctation patient who was successfully treated with a bare metal stent.
국형돈,홍나랑,이동헌,정혜정,안지영,박미연 대한피부과학회 2022 대한피부과학회지 Vol.60 No.6
Elastosis perforans serpiginosa (EPS) is a rare condition that belongs to the group of acquired perforating dermatosis. It usually appears as keratotic papules in serpiginous configuration with central atrophy on the head, nape, and extremities. It is characterized by the transepidermal elimination of elastic fibers with clumping and vertical orientation of elastic fibers. In many cases, it is associated with genetic or connective tissue diseases. A 26-year-old female patient with Down syndrome presented with brownish keratotic papules on both arms. The lesion had been present for 2 years, but there were no symptoms. The biopsy specimen showed transepidermal elimination of the degenerated elastic fibers. Verhoeff elastic staining revealed an increased number of thick elastic fibers. Based on these findings, the patient was diagnosed with EPS. Treatment with CO2 laser was performed with a successful outcome. (Korean J Dermatol 2022;60(6):387∼389)
국소성 단순 물집 표피박리증 환자에서 발생한 중증 건선 1예
정혜정,국형돈,이동헌,장동혁,배주윤,박미연,안지영 대한건선학회 2021 대한건선학회지 Vol.18 No.2
A 48-year-old man, who had a past and family history of blisters occurring on the hands and feet, visited our clinic with erythematous scaly plaques on the whole body. A biopsy on the foot showed a subepidermal blister with negative results in a direct immunofluorescence study, which was suggestive of epidermolysis bullosa simplex (EBS). Histological examination on the erythematous plaque was typically consistent with psoriasis. A biopsy on the abdomen showed histologic characteristics of both EBS and psoriasis. Therefore, he was diagnosed with psoriasis developed in localized EBS. Herein, we report a rare case of severe psoriasis vulgaris developed in a localized EBS patient.
Tuberculous Lymphadenitis in a Patient Treated with Dupilumab: A Case Report
이동헌,홍나랑,국형돈,정혜정,Mi Yeon Park,안지영 대한피부과학회 2023 Annals of Dermatology Vol.35 No.-
Tuberculous lymphadenitis is among the most frequent presentations of extrapulmonary tuberculosis; the most common presentation is isolated chronic non-tender lymphadenopa- thy in young adults without systemic symptoms. Dupilumab is a fully human monoclonal antibody directed against interleukin-4 receptor-α that blocks the synergistic effects of in- terleukin-4 and interleukin-13 on allergic inf lammation. Its well-known adverse events are allergic conjunctivitis, injection site reaction, and dupilumab facial redness. A 32-year-old female with severe atopic dermatitis was treated with dupilumab for 2 months at our clinic. She complained of multiple enlarged palpable lymph nodes on the right side of the neck and inguinal area for 2 months. Laboratory tests showed an increased total eosinophil count and immunoglobulin E level, as well as positive interferon-γ release assays. Radiological examination showed multiple low echoic and heterogeneous well-enhancing lymph nodes in level II, III, IV, and V of the neck. Histological examination revealed caseous necrosis and tuberculoid granuloma. The lymph node enlargements were completely relieved after anti- tuberculosis treatment. The mechanism for the development of tuberculous lymphadenitis in a patient receiving dupilumab is not fully understood yet. In some previous studies, treat- ment with dupilumab suppressed the expression of genes related not only to T helper 2 and eosinophil response but also to proinf lammatory responses. It could not inhibit the intra- cellular growth of Mycobacterium tuberculosis in macrophages, predisposing them to the development of tuberculous infection. To the best of our knowledge, this is the first report on the development of tuberculosis lymphadenitis in a patient treated with dupilumab.
Cutaneous Metastasis of Renal Cell Carcinoma Presenting as Multiple Nodules: A Case Report
이동헌,곽호은,박소윤,홍나랑,국형돈,안지영,박미연,정혜정 대한피부과학회 2024 대한피부과학회지 Vol.62 No.2
Renal cell carcinomas (RCC) account for 2.4% of all adult malignancies. RCC is known for its aggressive nature, with approximately one-third of patients presenting with metastasis at the time of diagnosis. Cutaneous metastasis is a rare presentation of this cancer. A 78-year-old male presented with numerous erythematous nodules of various sizes on the left flank, which he had had for a month. He had undergone a left partial nephrectomy for papillary RCC 3 years previously and had been receiving chemotherapy since surgery. Histopathology revealed papillary architecture with prominent atypical nucleoli throughout the dermis. Immunohistochemical findings were positive for CD10, cytokeratin 7, PAX-8, vimentin, and alpha-methylacyl-CoA racemase. These results led to a diagnosis of cutaneous metastases of papillary renal cell carcinoma. Papillary RCC rarely presents with cutaneous metastases. Because these lesions are easily accessible, cutaneous lesions in patients with risk factors for RCC should be excised and pathologically evaluated.