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Hobnail hemangioma occurred on the back
( Sang-myung Park ),( Joong-yoon Choi ),( Ye-jin Lee ),( Bark-lynn Lew ),( Woo-young Sim ) 대한피부과학회 2018 대한피부과학회 학술발표대회집 Vol.70 No.1
Hobnail hemangioma(HH) is a rare, vascular, benign solitary lesion of lymphatic origin. The typical clinical appearance is a single, annular, vascular lesion with a targetoid appearance. We report a case of 23-year-old female patient presenting with targetoid lesion on the back for 4 months. Physical examination revealed a solitary 1x1.5cm sized violaceous, slightly elevated papule surrounded 2x2.5cm sized round shaped ecchymotic ring on the back. Histopathologic findings of violaceous elevated papule revealed dilated, irregular vascular spaces in the papillary dermis. Peripheral areas showed dilated vessels with prominent plump endothelial cells with intraluminal papillary projections, showing a hobnail appearance in the papillary dermis. Deeper in the dermis, the vascular spaces were slit-shaped, angulated, and dissecting the collagen bundles. Immunohistochemical studies revealed that CD31 and D2-40 were expressed, but WT-1 was focally or weakly positive in the endothelial cells of the peripheral vessels showing a hobnail appearance. But, CD31, D2-40, and WT-1 were expressed in the endothelial cells of the central vessels. We diagnosed this case as a HH originating from a pre-existing hemangioma. Although the exact pathogenesis of HH is unknown, trauma is one of the main causes for the targetoid appearance. In our case, HH developed after trauma caused by friction from a clothing to a pre-existing hemangioma.
Florid papillomatosis on the nipple
( Sang-myung Park ),( Joong-yoon Choi ),( Ye-jin Lee ),( Bark-lynn Lew ),( Woo-young Sim ) 대한피부과학회 2018 대한피부과학회 학술발표대회집 Vol.70 No.1
Florid papillomatosis of the nipple (FP), also called adenoma of the nipple, is a rare, benign proliferative process of lactiferous ducts of the nipple. It is generally seen as a unilateral crusting of the nipple with serous, bloody, or serosanguinous discharge. A 35-year-old female presented with a crusting and unhealed lesion of her right nipple for the past 2 year. The physical examination revealed serous crust with an erythema on the right nipple and there was no ulceration and no regional lymphadenopathy. The left breast and nipple were normal. Histopathologic examination revealed a well circumscribed, proliferation of tubular glands within the nipple stroma. These tubules were lined by a peripheral layer of cuboidal cells and a luminal layer of columnar cells with secretory projections at the luminal border. Immunohistochemical study revealed that cuboidal cells in peripheral layer, myoepithelial cells, were positive for p63 and columnar cells in luminal layer, ductal epithelial cells, were positive for CK7, and focally positive for estrogen receptor. Based on these findings, she was diagnosed with FP. Recognition of FP is important because the lesions clinically may resemble Paget’s disease and histologically may be confused with well differentiated adenocarcinoma. Therefore, we should consider the histological features with immunohistochemical studies to diagnose FP. We report a rare FP located in the right nipple.
[P199] Epithelioid cell histiocytoma developed on palm
( Sang-myung Park ),( Min-jung Kang ),( Seung-hee Loh ),( Dong-woo Suh ),( Bark-lynn Lew ),( Woo-young Sim ) 대한피부과학회 2017 대한피부과학회 학술발표대회집 Vol.69 No.1
Fibrous histiocytoma is the most common cutaneous soft tissue lesions mainly located on the limbs and present as small, hyperkeratotic, cutaneous nodules. Epithelioid cell histiocytoma is one of the several variants of fibrous histiocytoma. Histologically, it is characterized as a well demarcated lesion composed of large epithelioid cells in the papillary and superficial reticular dermis. A49-year-old male presented with slowly increased mass on the left palm during 3 months. The physical examination revealed a well demarcated 1 x 1 cm sized dark brownish to flesh colored protruded mass on the left palm. Histopathologic examination revealed an infiltration of the papillary dermis by polygonal epithelioid cells with abundant eosinophilic cytoplasm. Lesional tissue was enclosed by collarettes of surface epithelium. There were abundant small blood vessels and a few multinucleated giant cells. Immunohistochemical study revealed that epithelioid cells were positive for CD31, CD68 and negative for S-100, CK AE1/3, CD1, CD34. Based onthese findings, he was diagnosed with epithelioid cell histiocytoma. The lesion was completely excised. Epithelioid cell histiocytoma has a broad differential diagnosis. Therefore, we should consider the histological features with immunohistochemical studies to diagnose epithelioid cell histiocytoma. We report a rare epitheloid cell histiocytoma located in the left palm, which is occurred in unusual site.
Histopathologic Features of Alopecia Areata: A Pathologic Approach to Prognosis
( Sang-myung Park ),( Joong-woon Choi ),( Bark-lynn Lew ),( Woo-young Sim ) 대한피부과학회 2020 大韓皮膚科學會誌 Vol.58 No.1
Background: Although alopecia areata (AA) is usually diagnosed based on the patient’s clinical manifestations, histologic features are the key to establishing the correct diagnosis. Moreover, it is possible to know about the progression of AA through understanding the various histologic characteristics of AA. Many studies have reported a lot of literatures related to AA, but studies investigating the correlation between histologic features and prognosis have not yet been reported. Objective: This study aimed to establish the histologic features of AA in scalp biopsy specimens and sought to correlate between histopathologic features and clinical prognosis. Methods: The pathology archives of Kyung Hee University Hospital at Gang-dong were searched for AA in the diagnostic field from the period of 2006 to 2016. The biopsy specimens were sectioned by Tyler technique. A total of 464 patients were included in the analysis. Results: There were reduction of anagen hair count according to the severity of AA, and a higher percentage of telogen ratio and vellus hair counts were observed in the alopecia totalis and alopecia universalis. Total hair counts (9.9) including miniaturized hairs were decreased prominently at more than 5 years of current duration. There was a high ratio of peribulge lymphocytic infiltration (45%) in patients with ophiasis and acute diffuse type and those with total alopecia showed prominent small portions of follicular miniaturization (27%). Conclusion: These histopathologic features mentioned above may shed light on the understanding of disease progression of AA, which have various clinical aspects. Using these histologic features, we will be able to predict the efficacy for therapy and prognosis of AA. (Korean J Dermatol 2020;58(1):26∼32)
Molluscum contagiosum occuring in an epidermal cyst developed on frontal hairline
( Sang-myung Park ),( Ki-hoon Kim ),( Joong-yoon Choi ),( Ye-jin Lee ),( Bark-lynn Lew ),( Woo-young Sim ) 대한피부과학회 2018 대한피부과학회 학술발표대회집 Vol.70 No.1
Molluscum contagiosum (MC) is a common skin infection due to the molluscum contagiosum virus (MCV). MCV may rarely infect keratinocytes of the hair follicle and a few cases of MC occurring in an epidermal cyst (EC) reported in the literature. An 8-year old girl presented with asymptomatic, solitary 1 x 1 cm sized, skin colored, subcutaneous nodules on the frontal hairline for several months. The patient had no known history or evidence at presentation of MCV lesions on the skin surface. On histologic examination, there were multiloculated cysts containing laminated horny material. The wall of the cyst contained all layers of the epidermis, including a granular layer. There were abundant eosinophilic inclusion bodies inside the cyst, dispersed among the keratinous contents, consistent with MCV cytopathic changes. She was diagnosed with MC occurring in an EC. The coexistence of MCV infection in an EC is an unusual presentation. The exact pathomechanism is not well known, but there are two hypotheses. One is coinoculation of MCV at the time of development of the EC, and the other is the invasion of MCV into a preexisting EC. Because there were not only changes of MCV infection through the entire lesion but also multiloculated changes with close approximation of the adjacent cystic components, it was considered that MC occurring in an EC was developed by the former pathomechanism.