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Methotrexate로 치료한 불응성 육아종성 유방염
유종진 ( Jong Jin Yoo ),강은하 ( Eun Ha Kang ),이윤종 ( Yun Jong Lee ),김성원 ( Sung Won Kim ),최인아 ( In Ah Choi ),이은봉 ( Eun Bone Lee ),송영욱 ( Yeong Wook Song ) 대한내과학회 2012 대한내과학회지 Vol.82 No.3
Granulomatous mastitis (GM) is an uncommon chronic inflammatory disease of the breast that can mimic breast carcinoma or infection. The treatment options include expectant management, complete resection, and corticosteroid therapy, although no standard treatment has been established. Recently, several case reports have suggested that methotrexate is another effective treatment for GM. Here, we describe the first Korean case of recurrent GM successfully treated with low-dose weekly methotrexate and review the relevant literature. (Korean J Med 2012;82:386-391)
급성관절염 환자에서 진단된 성인형 주기성 호중구감소증 1예
이명진 ( Myung Jin Lee ),유종진 ( Jong Jin Yoo ),강은하 ( Eun Ha Kang ),이상국 ( Sang Guk Lee ),신기철 ( Ki Chul Shin ),이은영 ( Eun Young Lee ),이은봉 ( Eun Bong Lee ),송영욱 ( Yeong Wook Song ),이윤종 ( Yun Jong Lee ) 대한류마티스학회 2013 대한류마티스학회지 Vol.20 No.1
Cyclic neutropenia (CN) is a rare disorder characterized by repetitive episodes of neutropenia and is generally associated with fever, oral mucosal ulcers, and bacterial infections in the neutropenic episodes. It usually manifests initially in infancy or childhood as an autosomal dominant or sporadic condition; however, adult-onset CN may have an autoimmune etiology. Here, we report the first case of a 22-year old man with CN in Korea. He developed acute arthralgia and fever 4 weeks after an episode of lower gastrointestinal symptoms. Serial blood cell counts showed recurrent neutropenia at 3 week intervals. Further, laboratory examination for neutropenia, including neutrophil elastase gene sequencing, did not reveal any abnormality. His arthritis and periarthritis fluctuated during his course. Under the diagnosis of CN, he received regular G-CSF therapy with partial improvement.
한국인 일차성 쇼그렌 증후군 환자의 선외 임상상의 분석
최병용 ( Byoong Yong Choi ),유종진 ( Jong Jin Yoo ),오혜진 ( Hye Jin Oh ),장유진 ( Yu Jin Jang ),이윤종 ( Yun Jong Lee ),송영욱 ( Yeong Wook Song ) 대한류마티스학회 2015 대한류마티스학회지 Vol.22 No.3
Objectives. To investigate the clinical findings upon initial diagnosis and extraglandular manifestations in Korean patients with primary Sjogren``s syndrome (pSS). Methods. We collected clinical and laboratory data from 238 pSS patients enrolled at Seoul National University Hospital, Seoul National University Bundang Hospital and Seoul Medical Center from March 2011 to December 2014. All patients met the American-European Consensus Group criteria for pSS. Results. Upon initial diagnosis, sicca symptoms (xerophthalmia or xerostomia) as the chief complaint were only observed in 129 (54.2%) pSS patients, while extraglandular manifestation was more common as the chief complaint in male patients or those with younger age (<40 years) than female or older patients (both p<0.05). Extraglandular manifestations were found in 178 (74.8%) patients, with musculoskeletal manifestations being most common (53.8%). Peripheral neuropathy in pSS patients was associated with Raynaud phenomenon and elevated serum total immunoglobulin G (IgG) levels (both p<0.05). Serum β2-microglobulin (β2-M) levels were significantly correlated with European League against Rheumatism (EULAR) Sjogren``s syndrome disease activity index, erythrocyte sedimentation rate and serum total IgG (all p<0.001), and were higher in patients with extraglandular manifestations than those without (p<0.05). Serum C3 levels were decreased in patients with extraglandular manifestation, compared to those without (p<0.05). Malignant lymphoma was found in Korean pSS patients (1.7%) and associated with elevated serum β2-M levels (p<0.0001). Conclusion. Extraglandular manifestations were common in pSS patients and may be a diagnostic tool for male or younger pSS patients. Serum β2-M levels can be useful markers for monitoring pSS patients. (J Rheum Dis 2015;22:167-174)
정희원 ( Hee Won Chung ),유종진 ( Jong Jin Yoo ),최병용 ( Byoong Yong Choi ),조현정 ( Hyun Jung Cho ),강은하 ( Eun Ha Kang ),송영욱 ( Yeong Wook Song ),이윤종 ( Yun Jong Lee ) 대한류마티스학회 2013 대한류마티스학회지 Vol.20 No.5
Primary Sjogren`s syndrome (pSS) is characterized by chronic inflammation and dysfunction in exocrine organs; however, it also has protean clinical features, including neuropsychiatric symptoms. A major neurological manifestation is peripheral neuropathy and involvement of the central nervous system is uncommonly described in pSS. A 52-year-old female was admitted because of depression, dysarthria, gait abnormality, and memory disturbance, which had developed over two months, and was diagnosed as pSS. She was treated successfully with high-dose glucocorticoid and cyclophosphamide pulse therapy without recurrence during the follow-up period of two years. Herein, we describe the first Korean case of pSS presenting with rapidly progressive cognitive impairment along with a review of the literature.
최재균 ( Jae Kyun Choi ),김경업 ( Kyung Up Kim ),박희수 ( Hee Su Park ),우지영 ( Ji Young Woo ),문수윤 ( Soo Yoon Moon ),오혜미 ( Hye Mi Oh ),유종진 ( Jong Jin Yoo ) 대한내과학회 2016 대한내과학회지 Vol.90 No.2
Retroperitoneal fibrosis (RPF) is a rare inflammatory fibrotic condition affecting the peri-aortic retroperitoneum in which fibrosis of the surrounding tissue can encase the ureters, resulting in obstructive uropathy. RPF is generally idiopathic in nature, but may also arise in response to other conditions, such as malignancies, infections, surgery, radiotherapy, or drugs. Idiopathic RPF is commonly seen in association with various autoimmune diseases, such as autoimmune thyroiditis, autoimmune pancreatitis, rheumatoid arthritis, and systemic lupus erythematosus (SLE). Here, we describe the first case of RPF in Korea. A 44-year-old man with SLE presenting with pain in both flanks due to RPF is discussed, along with a review of the relevant literature. (Korean J Med 2016;90:177-181)