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이승현(Seunghyun Lee),정석중(Sokjoong Chung),허진형(Jinhyung Heo),유혜린(Helen Lew) 대한안과학회 2018 대한안과학회지 Vol.59 No.11
목적: 기존 안와 황색육아종이 진단되었던 환자에서 재발된 피부 황색육아종을 통하여 면역글로불린G4관련안질환이 동반 진단된 증례를 보고하고자 한다. 증례요약: 양안의 눈꺼풀 부종을 주소로 38세 남성이 내원하였다. 전안부 및 후극부에서 특이 소견이 관찰되지 않았다. 조직검사상포말조직구 및 토우튼 거대세포가 관찰되며 S100 및 CD1 염색에 음성 소견을 보여 성인황색육아종 진단하 경구 아자씨오프린과 프레드리솔론 치료를 받았다. 4년 뒤 양안의 노란색 눈꺼풀 종괴를 주소로 재내원하였다. 자기공명영상에서 양안 안와 상외측의 대칭적인연부조직 부종이 관찰되었고, 혈액검사상 immunoglobulin G (IgG) 및 IgG4 수치가 상승되었다. 조직검사 후 면역화학염색에서IgG4+/IgG+ 10-20%, IgG4+ 22/고배율시야가 확인되었으며 과거 조직을 재염색하여 IgG4+/IgG+ 40-50%, IgG4+ 59/고배율시야를확인하여 전형적인 면역글로불린G4관련안질환으로 새롭게 진단하였다. 결론: 비특이적인 눈꺼풀 부종환자에서 면역글로불린G4관련안질환을 고려해야 하며, 기존 황색육아종 환자에서도 면역글로불린G4관련안질환이 동반될 수 있다. Purpose: To report a case of immunoglobulin G4 (IgG4)-related ophthalmic disease associated with adult xanthogranulomatous disease. Case summary: A 38-year-old male with a history of cholecystectomy visited our clinic for bilateral periorbital swelling. Histopathology of the orbital biopsy showed diffuse infiltration of foamy histiocytes with Touton giant cells and lymphoid follicles, with a diagnosis of adult-onset xanthogranuloma. After excisional biopsy, he was treated with azathioprine and prednisolone. Four years after treatment, he again visited the clinic due to bilateral, yellowish eyelid masses. Serological examinations were all nonspecific findings, except for elevation of IgG and IgG4 levels. Magnetic resonance imaging showed bilateral symmetric soft tissue enlargement with slightly heterogeneous T1/T2 isosignal intensity, with contrast enhancement at the superolateral aspect of extraconal spaces. Excisional biopsy and blepharoplasty were performed. Immunohistochemical sections showed that the IgG4+/IgG plasma cell ratio was 10-20% and the IgG4 plasma cell count was 22/high power field (HPF). His past sections of 2013 from the pathology department were again stained and showed that the IgG4+/IgG plasma cell ratio was 40-50% and the IgG4 plasma cell count was 59/HPF. Thus, he was definitely diagnosed with IgG4-related ophthalmic disease. Conclusions: If there is recurrent eyelid swelling, IgG4-related ophthalmic disease should be considered as a differential diagnosis. And the patient with adult xanthogranulomatous disease can be diagnosed with IgG4-related ophthalmic disease.
홍소담 ( So Dam Hong ),신재경 ( Jae Kyoung Shin ),홍희진 ( Hee Jin Hong ),허진형 ( Jin Hyung Heo ),정소영 ( So Young Chong ),오도연 ( Do Youn Oh ),오지수 ( Ji Su Oh ) 대한내과학회 2016 대한내과학회지 Vol.90 No.1
Most patients with recurrent uterine cervical cancer have intra-pelvis metastasis with adjacent lymph node involvement, while a lone, distant metastasis is extremely rare. We report a 79-year-old woman with recurrent uterine cervical cancer that presented as thyroid mass with no intra-pelvic recurrence. Four years earlier, the patient had been diagnosed with uterine cervical cancer. She had undergone a course of concurrent chemoradiotherapy to the pelvis and had no subsequent evidence of recurrence. Several weeks before presenting, she had noticed a foreign body sensation in her throat and a palpable mass in the left side of her neck. Clinically, this was metastatic squamous cell carcinoma from the uterine cervix. Patients who present with swelling or palpable nodules in the neck with a previously diagnosed malignancy must be evaluated for metastatic disease, although metastasis from uterine cervical carcinoma to the thyroid gland is rare. (Korean J Med 2016;90:68-71)
갑상선절제술을 시행 받은 고령의 갑상선암 환자의 임상적 특징에 대한 고찰
이근희(Keun Hee Lee)전학훈(Hak Hoon Jun),김종우(Jong Woo Kim),김승기(Seung Ki Kim),허진형(Jin Hyung Heo) 대한갑상선-내분비외과학회 2016 The Koreran journal of Endocrine Surgery Vol.16 No.4
Purpose: This study analyzes the clinical characteristics of thyroid cancer patients over 70 years of age following thyroidectomy. We identified the differences among previous studies and investigated the significance of thyroidectomy for elderly thyroid cancer patients. Methods: Information was abstracted from the charts of fifty-six patients treated during the period of Jan. 1995 to Dec. 2015. The abstraction included gender, age, surgical method, location with size of the main lesion, extent of lymph node metastasis, pathological features, gene mutation, complication, stage and most recent visit. Results: Our study showed a frequent occurrence (96.4% of the study group) of papillary thyroid cancers in elderly patients. There were three cases of postoperative complications. None had recurrence, and there was only one death due to complications of pneumonia. There were 11 advanced cases of cancer stage IV. Conclusion: Previous studies show that postoperative prognosis of elderly thyroid cancer patients is favorable. Average life expectancy is rising in South Korea, and therefore, the number of elderly thyroid cancer patients is increasing. Our study is meaningful in that it confirms the results of previous studies by surveying elderly patients over a 20 year period. It is deemed necessary that thyroidectomy be performed on elderly patients.