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심부정맥혈전증이 동반된 Churg-Strauss 증후군
정승민 ( Seung Min Chung ),이진희 ( Jin Hee Lee ),전준석 ( Jun Seok Jeon ),조아진 ( A Jin Cho ),정윤진 ( Yun Jin Jeung ),이병재 ( Byeoung Jae Lee ),최동철 ( Dong Chull Choi ),김태은 ( Tae Eun Kim ) 대한천식알레르기학회 2011 천식 및 알레르기 Vol.31 No.2
Churg-Strauss syndrome (CSS) is a rare multi-system vasculitis. Patients with CSS are at greater risk of venous thromboembolic events. However, venous thrombosis is rarely reported in patients with CSS in Korea. We report 1 patient with CSS who experienced deep vein thrombosis. A 27-year-old man was admitted to our hospital due to fever, cough, skin rash on both lower extremities, and right leg edema. He was diagnosed with CSS based on a history of asthma, peripheral eosinophilia, transient pulmonary infiltrates on chest radiograph, and extravascular eosinophils in the skin biopsy specimens. After steroid pulse therapy and the first cycle of intravenous pulse cyclophosphamide therapy, right leg edema did not resolve. Venous ultrasonography and CT angiography detected deep vein thrombosis involving the right common iliac, femoral and calf veins. The patient received both anticoagulation therapy and intravenous pulse cyclophosphamide therapy. After 6 months of anticoagulation therapy and the 9 cycles of intravenous pulse cyclophosphamide therapy, deep vein thrombosis completely resolved. (Korean J Asthma Allergy Clin Immunol 2011;31:148-152)
자각 증상과 심장비대 없이 심장 침범된 Churg-Strauss 증후군
김수아 ( Su A Kim ),안희경 ( Hee Kyung Ahn ),이수진 ( Su Jin Lee ),이준호 ( Jun Ho Yi ),정윤진 ( Yun Jin Jeung ),이병재 ( Byeoung Jae Lee ),최동철 ( Dong Chull Choi ) 대한내과학회 2010 대한내과학회지 Vol.78 No.2
We report a case of Churg-Strauss syndrome with cardiac involvement presenting without cardiomegaly or cardiopulmonary symptoms. A 47-year-old woman was referred to our institution for myalgia, peripheral numbness, and eosinophilia. She had been diagnosed with bronchial asthma and allergic rhinitis four years ago. The patient exhibited eosinophilia (71%) and elevated cardiac enzymes (cTnI, 2.977ng/mL). Cardiomegaly was not observed on chest radiography, but nonspecific ST segment changes were observed on electrocardiography. A transthoracic echocardiography revealed a dilated left ventricular cavity, a decreased left ventricle (42%), and diastolic dysfunction. Contrast-enhanced cardiac magnetic resonance imaging revealed delayed hyperenhancement 10 minutes after injecting gadolinium. An endomyocardial biopsy showed eosinophilic myocarditis associated with vasculitis. The patient was diagnosed with Churg-Strauss syndrome and received combination therapy with steroid and cyclophosphamide. After the second treatment cycle, the blood eosinophilia disappeared and the vasculitis and infiltration of eosinophils into the endomyocardial tissue had completely resolved. (Korean J Med 78:266-272, 2010)