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위장관 간질 종양으로 Sunitinib치료 후 빠른 반응과 함께 발생한 장관기종 및 장천공 1례
곽형종 ( Hyoung Jong Kwak ),김경민 ( Kyoung Min Kim ),김민호 ( Min Ho Kim ),진공용 ( Gong Yong Jin ),정명자 ( Myoung Ja Chung ) 전북대학교 의과학연구소 2011 全北醫大論文集 Vol.35 No.1
Pneumatosis intestinalis is an unusual intestinal pathology that is characterized by the presence of gas within the intestinal wall, usually in the mucosa or submucosa of the small or large intestine. Sunitinib is a small molecule that inhibits multiple receptor tyrosine kinases such as KIT, vascular endothelial growth factor (VEGF) and platelet-derived growth factor (PDGF). It is use das second-line therapy for patients with imatinib-resistant gastrointestinal stromal tumors (GIST).We report here a 61-year-old male patient diagnosed with recurrent GIST complicated by massive peritoneal metastasis involving the small intestine, with resistance to imatinib. Following rapid response to sunitinib treatment, pneumatosis intestinalis of the small intestine occurred and led to perforation at a previous anastomotic site. In conclusion, the possibility of pneumatosis intestinalis and intestinal perforation associated with rapid response should be considered during antiangiogenic therapy in patients with malignancies involving the gastrointestinal tract.
Klinefelter 증후군 환자에서 진단된 전신성 홍반성 루프스 1예
곽형종 ( Hyoung Jong Kwak ),장규윤 ( Kyu Yun Jang ),정명자 ( Myoung Ja Chung ),문우성 ( Woo Sung Moon ),강명재 ( Myoung Jae Kang ),이동근 ( Dong Geun Lee ),박호성 ( Ho Sung Park ) 전북대학교 의과학연구소 2011 全北醫大論文集 Vol.35 No.1
저자들은 전신성홍반성루푸스와 Klinefelter증후군을 동시에 진단하였던 1예를 경험하였기에 보고하는 바이다. We report a case of SLE related epistaxis(due to thrombocytopenia) in a 16 year-old man with Klinefelter`s syndrome. Clinical outcome was favorable with low doses of corticosteroids. The incidence of systemic lupus erythematosus(SLE) is known to be affected by sex hormone. Patients with Klinefelter`s syndrome were reported to have abnormal sex hormonal metabolism and their chronic estrogenic stimulation seems to affect the pathogenesis of SLE. Therefore, association of SLE and Klinefelter`s syndrome has been considered as a clue of the effect of sex hormone on SLE.
불완전 비틀림을 보인 줄기를 가진 가슴막밑 지방종 1예 보고
곽형종 ( Hyoung Jong Kwak ),차은정 ( Eun Jung Cha ),손경락 ( Kyung Rak Sohn ),구자홍 ( Ja Hong Kuh ),진공용 ( Gong Yong Jin ),정명자 ( Myoung Ja Chung ),장규윤 ( Kyu Yun Jang ) 대한내과학회 2008 대한내과학회지 Vol.74 No.6
Lipoma is a common benign neoplasm, but lipoma arising from the pleura is rare. Most pleural lipomas are asymptomatic and are discovered incidentally on chest radiographs. Here we report an unusual case of a pedunculated subpleural lipoma with incomplete torsion in a 29-year-old woman who presented with flank pain. On chest radiography, there was a well-defined, ellipsoidal, homogeneous, radioopaque mass in the left lower lobe. An intrathoracic tumor was suspected, and video-assisted thoracic surgery was performed to establish the final diagnosis. The resected tumor was a 10×5 cm sized pedunculated pleural mass. The cut surface showed a yellow, well-circumscribed mass with areas of hemorrhage. Histologically, the tumor was composed of mature adipose tissue with fibrous septae composed of fibroblasts. The outer surface of the tumor was covered by mesothelial cells. Some areas were hypercellular, and occasional mitoses were found, but neither lipoblasts nor atypical mitoses were identified.(Korean J Med 74:676-679, 2008)