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Single pleural relapse of a nasal -type extranodal natural killer/ T-cell lymphoma
( Ys Jeong ),( Sw Kim ),( Sn Lim ),( Sy Choi ),( Oj Lee ),( Kh Choe ),( Gm Lee ),( Jy An ) 대한내과학회 2013 대한내과학회 추계학술발표논문집 Vol.2013 No.1
Extranodal natural killer (NK)/T-cell lymphoma is a subtype of lymphoma that is derived from NK cells and is relatively more common in Asia than in Western countries. NK/T-cell lymphoma considered an aggressive form of non-Hodgkin`s lymphoma (NHL). Approximately half of all patients relapse during the follow-up period, and relapsed NK/T-cell lymphoma patients often show a fulminant clinical course that is refractory to conventional chemotherapy treatments. This accounts for the early sharp drop in the overall survival curves of extranodal NK/T-cell lymphoma patients. Most relapses of NK/T-cell lymphoma occur within the first 2 years of remission. However, rare cases of relapse in NK/T-cell lymphoma, nasal type have been described after many years of remission. Such late relapses are so rare that practically nothing is known about them. We describe an unusual case of a 42-year-old man who experienced recurrence after 8 years of remission. The patient presented with pleural effusion involving Epstein-Barr virus (EBV)-positive NHL Cells of the NK/T-cell lineage. In this case study, NK/T-cell lymphoma recurred with tuberculosis-like symptoms and left pleural effusion after 8 years of remission. The tumor clinically mimicked pulmonary tuberculosis as it presented with pleural effusion without lymphadenopathy, organomegaly, or an extranodal mass. Pleural fluid analysis revealed exudates with a predominance of lymphomcytes and high adenosine deaminase (ADA) levels.