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고혈압 과거력이 없는 여성에서 출산 후 신동맥 파열로 발견된 양측 신동맥 섬유근이형성증 1예
김은은 ( Eun-eun Kim ),원유동 ( Yoodong Won ),김연희 ( Yeon-hee Kim ),신인혜 ( Inhye Shin ),김영옥 ( Young Ok Kim ) 대한내과학회 2021 대한내과학회지 Vol.96 No.5
Fibromuscular dysplasia (FMD) of the renal artery is a non-atherosclerotic, non-inflammatory vascular disease that causes stenosis, aneurysm, dissection, and occlusion of the vessel. We report a rare case of a postpartum FMD patient who presented with spontaneous acute perirenal hematoma due to renal artery aneurysm rupture after cesarean section. The 40-year-old patient presented with sudden onset of abdominal pain 2 days after an elective cesarean section performed at full gestational term. A computed tomography scan of the abdomen revealed perirenal hematomas with signs of FMD in both renal arteries. The bleeding was successfully controlled by transcatheter arterial embolization. Short-term continuous renal replacement therapy was performed until her renal function recovered. FMD of the renal artery is rare in pregnant patients. Additionally, aneurysm rupture can be life threatening and requires immediate medical attention and prompt management. (Korean J Med 2021;96:438-442)
최지연 ( Jiyeon Choi ),김영옥 ( Young Ok Kim ),원유동 ( Yoodong Won ),나세정 ( Sae Jung Na ) 대한내과학회 2020 대한내과학회지 Vol.95 No.3
Flash pulmonary edema is characterized by a sudden episode of dyspnea resulting from acute pulmonary venous congestion, which resolves rapidly. We report a case of renal artery stenosis presenting as flash pulmonary edema in a patient with solitary kidney treated by angioplasty with stent implantation. A 75-year-old man with solitary kidney visited the emergency room with acute shortness of breath. His blood pressure had risen to 206/90 mmHg and a chest radiograph revealed pulmonary edema. Echocardiography and coronary arteriography showed no clear abnormalities, but abdominal computed tomography revealed severe focal stenosis in the left proximal renal artery. A captopril renal scan found that the time to peak and half-time of radioactivity were delayed in the left kidney. Percutaneous transluminal angioplasty was performed, followed by stent implantation. After this procedure, the stenotic segment was completely dilated and blood pressure returned to the normal range. (Korean J Med 2020;95: 205-210)
혈액투석 환자에서 유전성출혈모세혈관확장증에 의한 폐동정맥기형
박세영 ( Seyoung Bahk ),부성현 ( Seong Hyeon Bu ),김형덕 ( Hyung Duk Kim ),원유동 ( Yoodong Won ),이해규 ( Hae Giu Lee ),김영옥 ( Young Ok Kim ) 대한내과학회 2021 대한내과학회지 Vol.96 No.3
Hereditary hemorrhagic telangiectasia (HHT) is an uncommon autosomal dominant disorder resulting in vascular malformation, such as pulmonary arteriovenous malformation (PAVM). Here, we report a rare case of pulmonary arteriovenous malformation caused by HHT in a hemodialysis (HD) patient. A 34-year-old man receiving maintenance HD via radiocephalic arteriovenous fistula developed progressive dyspnea without definite pulmonary edema. His mother had been diagnosed with HHT. He had experienced multiple episodes of epistaxis and had been intermittently treated with blood transfusions because of severe anemia. Blood gas analysis showed hypoxia. Chest computed tomography revealed multiple dilated vessels of variable sizes, continuous with the pulmonary artery throughout both lung fields, consistent with PAVM. After treating pulmonary artery embolization at the largest PAVM, he recovered from his dyspnea symptoms and hypoxia. (Korean J Med 2021;96:247-251)