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다발성 간 전이를 보인 글루카곤종에서 Sunitinib 치료 후 발생한 중성구감소증
문홍란 ( Hong Ran Moon ),최지민 ( Ji Min Choi ),장동기 ( Dong Kee Jang ),이민종 ( Minjong Lee ) 대한내과학회 2013 대한내과학회지 Vol.84 No.3
Pancreatic neuroendocrine tumors (PNET) are rare, with approximately 2.2 in 1,000,000 people affected annually. In the classification of neuroendocrine tumors, glucagonomas are a functional PNET and comprise 1.6% of PNET. Glucagonoma syndrome is a paraneoplastic syndrome that is characterized by necrolytic migratory erythema, weight loss, anemia, and diabetes mellitus. Metastatic disease at presentation is common, but is often limited to the liver and regional lymph nodes. Sunitinib malate improves the progression-free and overall survival of PNET. This report presents a 45-year-old Asian woman with prolonged neutropenia after sunitinib treatment of a glucagonoma with multiple hepatic metastases. The severity of the neutropenia after the sunitinib treatment fluctuated from grade 1 to 4 repeatedly, with a non-febrile pattern. Ultimately, the patient did not recover from the neutropenia, even after stopping the sunitinib. (Korean J Med 2013;84:405-410)