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A case of atypical adult onset Still`s disease that presented with unique histopathologic findings
( Dongjoo Kim ),( Dongyeup Lee ),( Sookyung Lee ),( Myoungshin Kim ),( Unha Lee ),( Jeonghee Hahm ) 대한피부과학회 2015 대한피부과학회 학술발표대회집 Vol.67 No.1
Adult-onset Still’s disease (AOSD) is an uncommon systemic inflammatory disorder characterized by fever, polyarthralgia, elevated white blood cell count, and a distinctive erythematous rash according to the diagnostic criteria of Yamaguchi. The typical skin rash in AOSD is an evanescent, erythematous maculopapular lesion, associated with non-specific histopathologic features such as perivascular inflammatory infiltration. However, other skin lesions such as persistent pruritic papules and plaques are rarely seen in AOSD. A 54-year-old woman presented with fever, arthritis, persistent pruritic lichenified patches. Skin biopsy showed dyskeratosis with a peculiar, distinctive distribution in the upper epidermis and cornified layers with hyperkeratosis. In addition, increased dermal mucin was present, with minimal fibroblast proliferation and inflammation. She was diagnosed with AOSD according to the diagnostic criteria of Yamaguchi. Herein, We present an atypical form of AOSD(persistent pruritic papules and plaques), showing clinically and pathologically distinctive manifestation.
A case of subungual amelanotic melanoma
( Hoyoung Kim ),( Jaeho Lee ),( Joongheon Suh ),( Sookyung Lee ),( Unha Lee ),( Myoungshin Kim ) 대한피부과학회 2019 대한피부과학회 학술발표대회집 Vol.71 No.1
Subungual amelanotic melanoma is rare, only 15-25% of subungual melanoma. Since it appears pinkish or reddish, early diagnosis is often delayed causing poor prognosis. It usually occurs in thumbs or great toes. Pathogenesis of amelanotic melanoma is not well elucidated, but lack of tyrosinase and agenesis of melanosomes are possible causes. A 67-year-old male had subungual erythematous papule on his left thumb. It appeared 10 years ago and had increased in size splitting the nail. At the first visit, the lesion had discharge smelling foul odor. The biopsy specimen of nail plate showed several hyperchromatic large cells in epidermis and nail plate. In immunohistochemistry, Melan-A was focally positive and p63 was negative. The specimen of nail bed showed hyperchromatic and pleomorphic cells with positivity for Melan-A and negativity for pan-cytokeratin. He underwent excisional biopsy and the specimen showed atypical melanocytes in epidermis and nests of numerous hyperchromatic cells with mitotic figures in dermis. He was diagnosed with subungual amelanotic melanoma with pathologic stage T3b.
Verruca plana developing after semipermanent tattooing
( Dongjoo Kim ),( Dongyeup Lee ),( Sookyung Lee ),( Myoungshin Kim ),( Unha Lee ),( Jeonghee Hahm ) 대한피부과학회 2015 대한피부과학회 학술발표대회집 Vol.67 No.1
Tattooing for cosmetic adornment is becoming more popular around the world. Yet there are many complications associated with the introduction of pigment into skin, such as local inflammation, allergic reactions and infection. The infectious side effects include local bacterial infections and transmission of hepatitis, syphilis and human immunodeficiency virus (HIV). A 21-year-old healthy man presented with multiple flesh verrucous papules on forearms after undergoing semipermanent tattooing. Histologic examination of the cutaneous lesion showed acanthosis and koilocytosis that are typical of verruca plana. Proliferation of dilated capillaries was present within the papillary dermis. The tattooing had been done 2 years earlier by an amateur. Herein, We report a case of verruca plana that developed after semipermanent tattooing.
A case of pigmented spindle cell nevus with an unusual dermoscopic feature
( Dongjoo Kim ),( Dongyeup Lee ),( Sookyung Lee ),( Myoungshin Kim ),( Unha Lee ),( Jeonghee Hahm ) 대한피부과학회 2015 대한피부과학회 학술발표대회집 Vol.67 No.1
Pigmented spindle cell nevus (PSCN, Reed nevus) is a solitary heavily pigmented macule or papule that usuallyoccurs on the lower legs of women in the second decade of life. Histologically, fascicles of uniform, elongated, pigmented nevoid cells at the dermo-epidermal junction tend to fuse with neighboring nests. Three main dermoscopic patterns of PSCN are starburst, globular, atypical pattern. Also, very few cases of PSCN with peripheral reticular pattern have been reported. Our patient was a 49-year old female presented with a 1-year history of black ovoid papule on the right second finger. Dermoscopic examination of the lesion showed a brown to black diffuse pigmentation with discrete depigmentations in the center of the lesion. At the periphery of the lesion, the streaks radiated in the direction of the normal skin, forming a relatively uniform network, characteristic of “peripheral reticular” dermoscopic pattern. Histopathologic examination revealed the typical histologic features of PSCN. There was no atypical feature such as mitoses or pleomorphism. Herein, we report a case of pigmentedspindle cell nevus with the unusual dermoscopic feature.
A case of primary cutaneous diffuse large B-cell lymphoma with multifocal subcutaneous lesions
( Dongjoo Kim ),( Sookyung Lee ),( Joongheon Seo ),( Myoungshin Kim ),( Unha Lee ) 대한피부과학회 2016 대한피부과학회 학술발표대회집 Vol.68 No.1
In the WHO-EORTC (World Health Organization-European Organization for Research and Treatment of Cancer) classification, the primary cutaneous B-cell lymphomas were divided into 4 groups. Among them, primary cutaneous diffuse large B-cell lymphoma, leg type (PCLBCL LT) is a very unique entity in that it predominantly affects elderly patients and presents as rapidly progressing nodules or tumors confined to legs or rarely on other body parts. A 82-year-old woman presented with rapidly growing multiple subcutaneous nodules in her both upper eyelid, right chest and back. Microscopic examination of skin biopsy specimen showed diffuse infiltrates of large atypical lymphocytes with vesicular nuclei, prominent nucleoli and moderate degree of mitotic figures in deep dermis and subcutis. They were largely composed of centroblast- and immunoblast-like cells. Immunophenotypic studies revealed the lymphoid infiltrates reacted with CD20, bcl-2 and bcl-6 protein, but none of the sections expressed CD3, CD10, CD30 and Ebstein-Baar Virus in situ hybridization. In physical examination and staging work-up, we could not find any other extracutaneous or systemic involvement. The patient was diagnosed with DLBCL and was treated with 3 cycles of high-dose multiagent chemotherapy with the anti-CD20 monoclonal antibodies. Herein, we report a case of primary cutaneous diffuse large B-cell lymphoma with multifocal skin lesions.
A case of basal cell carcinoma on the vulva
( Hoyoung Kim ),( Jaeho Lee ),( Joongheon Suh ),( Sookyung Lee ),( Unha Lee ),( Myoungshin Kim ) 대한피부과학회 2019 대한피부과학회 학술발표대회집 Vol.71 No.1
Basal cell carcinoma (BCC) is the most common non-melanoma skin cancer. Ultraviolet is a well known carcinogen, but activation of Hedgehog signaling pathway is another main cause for BCC carcinogenesis. BCC typically arises in sun-exposed areas such as the head and neck. Vulvar or perianal BCC has uncommonly been reported. A 70-year-old female presented with a black annular plaque on her right vulva 3 years ago. It had increased in size and itched. The skin biopsy revealed groups of basaloid cells with clefting artifact in dermo-epidermal junction. Peripheral palisading in the lesion was also obvious. She was diagnosed with basal cell carcinoma and underwent wide excision. Herein, we report an unusual case of basal cell carcinoma arising in the vulva.
( Dongjoo Kim ),( Dongyeup Lee ),( Sookyung Lee ),( Myoungshin Kim ),( Unha Lee ),( Jeonghee Hahm ) 대한피부과학회 2015 대한피부과학회 학술발표대회집 Vol.67 No.1
Poroid hidradenoma is a benign tumor that belongs to the group of poroid neoplasms and so-called because of its morphology intermediate between a cytological features of poroid neoplasm (poroid and cuticular cells), and architectural features of hidradenoma (solid and cystic areas and tumor cells entirely restricted to the dermis). Clinically, it is relatively rare and usually asymptomatic, dome-shaped, round to oval nodule with reddish to bluish colors. The head and neck are known to be the most common involved site, though it may involve any parts of the body. As they are cystic and superficially located, fine needle aspiration cytology has been useful, but the diagnosis relies on the histological examination. A 79-year-old woman presented with solitary walnut-sized, soft, tender, reddish to bluish nodular lesion which had been enlarging steadily over a period of two years. Histopathologic examination of the cutaneous lesion showed solitary well-demarcated multi-lobular tumor composed of the cystic and solid components in the dermis without direct connection to the overlying epidermis. The tumor consisted of poroid and cuticular cells without atypical feature such as mitoses or pleomorphism. On immunohistochemical staining, some tumor cells were positive for EMA, PAS. Herein, We present a rare case of poroid hidradenoma arising in an unusual location.
A case of latanoprost-induced diffuse facial skin pigmentation
( Hoyoung Kim ),( Joongheon Suh ),( Sookyung Lee ),( Myoungshin Kim ),( Unha Lee ) 대한피부과학회 2018 대한피부과학회 학술발표대회집 Vol.70 No.1
Latanoprost is a prostaglandin F2α analogue, which has been used as the first choice of drug for an open angle glaucoma. The common side effects of latanoprost include conjunctival hyeperemia, iris hyperpigmentation and periouclar skin pigmentation. A 71-year-old female was presented with diffuse brownish to gray maculopatches on her face. The symptom appeared 1 year and 4 months ago when she started to use latanoprost for an open angle glaucoma of her both eyes. The blood test was normal. The biopsy specimen revealed vaculoar degeneration at dermo-epidermal junction and pigment incontinence in the dermis. The patient discontinued latanoprost and was treated with laser therapies. After 4 months, the pigmentation became lighter and the patient was satisfied with the change. In most cases, latanoprost-induced skin pigmentation was limited in periocular skin. However, it can occur extensively or in the entire face. Herein, we report a rare case of diffuse facial skin pigmentation after use of latanoprost.